Introduction: Urinary tract paragangliomas account for less than 1% of all paragangliomas and are most commonly seen in the bladder, with the prostate being the second most common localization. However, urethral paragangliomas are extremely rare. Case Presentation: A 52-year-old male patient was admitted to the urology clinic with lower urinary tract symptoms (LUTS), including poor and intermittent stream, straining, frequency, and nocturia. A pedunculated polypoid lesion, approximately 1 cm in size, was detected at the level of the bulbar urethra and was excised from its stalk using cold cup forceps. A diagnosis of paraganglioma was made on histopathological examination. Conclusion: Anterior urethral paraganglioma can cause LUTS even if small due to urethral calibration. The recommended treatment method is endoscopic excision of the lesion. Paraganglioma should be kept in mind in the differential diagnosis of urethral lesions.

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